case_images: PMC4860917_01
case_images: Extra orally diffuse swelling over the right maxillary sinus extending onto the ala of nose
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case_images: F1
case_images: Extraorally, the patient had diffuse swelling over the right maxillary sinus region extending over the ala of the nose [Figure 1].
case_images: Intraoral examination revealed unhealed socket of 17 surrounded by everted margins and necrosed bone within
case_images: JOMFP-20-142-g002.jpg
case_images: PMC4860917_01_JOMFP-20-142-g002.jpg
case_images: F2
case_images: Intraorally, there was an unhealed socket of 17 with necrosed bone inside, surrounded by everted margins [Figure 2].
case_images: Contrast-enhanced computed tomography exhibiting nonhomogeneous enhancing lesion destroying walls of maxillary and ethmoid sinus, upper right alveolus and extending into masticator space and infratemporal region
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case_images: PMC4860917_01_JOMFP-20-142-g003.jpg
case_images: F3
case_images: No cervical lymphadenopathy was evident [Figure 3].
case_images: Basaloid islands and cord-like structures infiltrating the overlying epithelium, areas of mucous cells and mucin filled spaces are also seen (H&E stain, x40)
case_images: JOMFP-20-142-g004.jpg
case_images: PMC4860917_01_JOMFP-20-142-g004.jpg
case_images: F4
case_images: These structures were seen infiltrating into the overlying epithelium [Figure 4] and showed two cell populations: peripheral tall columnar and central round to ovoid cells.
case_images: Peripheral palisaded arrangement of columnar cells and central loose cells showing stellate reticulum-like appearance with interspersed mucous cells (H&E stain, x400)
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case_images: PMC4860917_01_JOMFP-20-142-g005.jpg
case_images: F5
case_images: Some of the central areas showed the presence of mucous cells and mucin filled spaces [Figure 5].
case_images: Tumour cells forming canalicular and tubular structures enclosing haemorrhagic spaces (H&E stain, x100)
case_images: JOMFP-20-142-g006.jpg
case_images: PMC4860917_01_JOMFP-20-142-g006.jpg
case_images: F6
case_images: At places, the tumor cells formed canalicular structures enclosing hemorrhagic spaces [Figure 6].
case_images: Calretinin negativity ruled out ameloblastoma (IHC stain, x400)
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case_images: F7
case_images: Negative immunostaining for calretinin ruled out ameloblastoma [Figure 7].
case_images: Periodic acid-Schiff (PAS) stain positivity at periphery of islands and cytoplasm of central cells (PAS stain, x400)
case_images: JOMFP-20-142-g008.jpg
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case_images: F8
case_images: Periodic acid-Schiff stain revealed patchy positivity at the periphery of islands and in the cytoplasm of the central cells indicating a salivary gland origin [Figure 8].
case_images: Calponin immunostaining shows strongly positive peripheral cells of the lesion suggestive of myoepithelial cells (IHC stain, x400)
case_images: JOMFP-20-142-g009.jpg
case_images: PMC4860917_01_JOMFP-20-142-g009.jpg
case_images: F9
case_images: On immunostaining, strong positivity for calponin in the peripheral basaloid cells was suggestive of myoepithelial cells [Figure 9].
case_images: CK 19 showed patchy positivity in the center of islands at places and the tubular structures (IHC stain, x400)
case_images: JOMFP-20-142-g010.jpg
case_images: PMC4860917_01_JOMFP-20-142-g010.jpg
case_images: F10
case_images: Cytokeratin (CK 19) positivity in the central cells and cells in cords was suggestive of luminal cells [Figure 10].
case_images: Ki-67 index <5% (IHC stain, x400)
case_images: JOMFP-20-142-g011.jpg
case_images: PMC4860917_01_JOMFP-20-142-g011.jpg
case_images: F11
case_images: Ki-67 index was <5% [Figure 11].